Aim

To present a case of inflammatory odontogenic cyst with unusual imaging presentation.

Clinical case

A 13-year-old female patient, with no history of morbidity, with a radiographic finding of a mixed lesion located between the lower right premolars. The patient visited the professional Oral Pathology clinic of the Andrés Bello University and was referred to postgraduate oral and maxillofacial surgery for an excisional biopsy of the lesion, with a diagnostic hypothesis of adenomatoid odontogenic tumor. After the histopathological study, the lesion was defined as an inflammatory odontogenic cyst, which, based on clinical- radiographic characteristics, could be a residual cyst of a primary tooth.

Due to the variability in the clinical and imaging presentation of maxillofacial cystic lesions, anatomopathological study is essential for correct diagnosis and treatment.